NYMC Faculty Publications

Contemporary Biology, Management, and Outcomes of Renal Medullary Carcinoma in Children and Adults: A Pediatric Surgical Oncology Research Collaborative Study

Authors

Catherine B. Beckhorn, Duke University School of Medicine
Marcus M. Malek, UPMC Children’s Hospital of Pittsburgh
Harold N. Lovvorn, Vanderbilt University Medical Center
Harold J. Leraas, Duke University Medical Center
Katlyn G. McKay, Vanderbilt University Medical Center
Nelly Ange T. Kontchou, Vanderbilt University Medical Center
Zachary J. Kastenberg, University of Utah School of Medicine
David W. Hoyt, University of Utah School of Medicine
Jonathan P. Roach, University of Colorado School of Medicine
Emily K. Myers, University of Colorado School of Medicine
Nicholas G. Cost, University of Colorado School of Medicine
Bhargava Mullapudi, Children's Mercy Research Institute (CMRI)
Charles R. Marchese, Children's Mercy Research Institute (CMRI)
Amanda R. Jensen, Children's Mercy Research Institute (CMRI)
Timothy B. Lautz, Northwestern University Feinberg School of Medicine
Michela Carter, Northwestern University Feinberg School of Medicine
Roshni Dasgupta, Cincinnati Children's Hospital Medical Center
John Lundstedt, Cincinnati Children's Hospital Medical Center
Joseph G. Brungardt, Cincinnati Children's Hospital Medical Center
Lindsay J. Talbot, St. Jude Children's Research Hospital
Andrew M. Davidoff, St. Jude Children's Research Hospital
Andrew J. Murphy, St. Jude Children's Research Hospital
Jennifer H. Aldrink, The Ohio State University College of Medicine
Sara A. Mansfield, The Ohio State University College of Medicine
Nelson Piché, CHU Sainte-Justine - Le Centre Hospitalier Universitaire Mère-Enfant
Dave R. Lal, Medical College of Wisconsin
Brian T. Craig, Medical College of Wisconsin
Jennifer M. Schuh, Medical College of Wisconsin
Barrett P. Cromeens, Indiana University School of Medicine
Sindhu V. Mannava, Indiana University School of Medicine
Shannon L. Castle, Valley Children's Hospital
Adriana Lopez, Valley Children's Hospital

Author Type(s)

Faculty

DOI

10.1002/pbc.31774

Journal Title

Pediatric Blood and Cancer

Document Type

Article

Publication Date

8-1-2025

Department

Surgery

Keywords

pediatric cancer, pediatric surgical oncology, renal cancer, renal medullary carcinoma, sickle cell

Disciplines

Medicine and Health Sciences

Abstract

Background: Renal medullary carcinoma (RMC) is an aggressive tumor associated with sickle cell trait. Despite treatment advances for other rare renal tumors, RMC survival remains poor. We aimed to describe the contemporary management and survival of children and adults with RMC. Procedure: In this multicenter retrospective cohort study, Pediatric Surgical Oncology Research Collaborative sites searched their databases for patients diagnosed with RMC (2000–2022). Descriptive statistics were calculated and survival analyses performed using Kaplan–Meier and Cox regression. Results: Thirty-four patients with RMC were identified. Median age was 19 years (IQR: 15–28; range: 7–52). Most were male (24/34; 71%), Black (27/32; 84%), had sickle cell trait or disease (30/33; 91%), presented with metastatic disease (27/34; 79%), and were symptomatic at presentation (32/34; 94%). Median overall survival (OS) was 24 months from diagnosis (16 months for children, 28 months for adults, p = 0.6). Receipt of platinum-based chemotherapy (23/34; 68%) was associated with significantly higher OS than other regimens (35 vs. 5 months, p < 0.001). Nephrectomy (24/34; 71%) was associated with significantly improved OS compared with non-operative management (34 vs. 7 months, p = 0.001). Immunotherapy, targeted therapy, or radiation therapy were not associated with significant differences in OS, nor were age, sex, race, sickle cell status, SMARCB1/INI-1, stage, nephrectomy approach, retroperitoneal lymph node dissection, gross residual disease, margins, or tumor size. Conclusions: RMC survival remains poor despite newer therapies. Nephrectomy and platinum-based chemotherapy should be considered in locally advanced and metastatic disease. Coordinated international cooperative group studies are needed to meaningfully improve RMC survival.

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